Principles and Methods for Assessing Direct Immunotoxicity

Associated with Exposure to Chemicals

1. INTRODUCTION TO IMMUNOTOXICOLOGY

1.1. Historical overview

1.2. The immune system; functions, system regulation, and

modifying factors; histophysiology of lymphoid organs

1.2.1. Function of the immune system

1.2.1.1 Encounter and recognition

1.2.1.2 Specificity

1.2.1.3 Choice of effector reaction; diversity

of the answer

1.2.1.4 Immunoregulation

1.2.1.5 Modifying factors outside the immune

system

1.2.1.6 Immunological memory

1.2.2. Histophysiology of lymphoid organs

1.2.2.1 Overview: structure of the immune system

1.2.2.2 Bone marrow

1.2.2.3 Thymus

1.2.2.4 Lymph nodes

1.2.2.5 Spleen

1.2.2.6 Mucosa-associated lymphoid tissue

1.2.2.7 Skin immune system or skin-associated

lymphoid tissue

1.3. Pathophysiology

1.3.1. Susceptibility to toxic action

1.3.2. Regeneration

1.3.3. Changes in lymphoid organs

2. HEALTH IMPACT OF SELECTED IMMUNOTOXIC AGENTS

2.1. Description of consequences on human health

2.1.1. Consequences of immunosuppression

2.1.1.1 Cancer

2.1.1.2 Infectious diseases

2.1.2. Consequences of immunostimulation

2.2. Direct immunotoxicity in laboratory animals

2.2.1. Azathioprine and cyclosporin A

2.2.1.1 Azathioprine

2.2.1.2 Cyclosporin A

2.2.2. Halogenated hydrocarbons

2.2.2.1

2,3,7,8-Tetrachlorodibenzo- para-dioxin

2.2.2.2 Polychlorinated biphenyls

2.2.2.3 Hexachlorobenzene

2.2.3. Pesticides

2.2.3.1 Organochlorine pesticides

2.2.3.2 Organophosphate compounds

2.2.3.3 Pyrethroids

2.2.3.4 Carbamates

2.2.3.5 Dinocap

2.2.4. Polycyclic aromatic hydrocarbons

2.2.5. Solvents

2.2.5.1 Benzene

2.2.5.2 Other solvents

2.2.6. Metals

2.2.6.1 Cadmium

2.2.6.2 Lead

2.2.6.3 Mercury

2.2.6.4 Organotins

2.2.6.5 Gallium arsenide

2.2.6.6 Beryllium

2.2.7. Air pollutants

2.2.8. Mycotoxins

2.2.9. Particles

2.2.9.1 Asbestos

2.2.9.2 Silica

2.2.10. Substances of abuse

2.2.11. Ultraviolet B radiation

2.2.12. Food additives

2.3. Immunotoxicity of environmental chemicals in wildlife and

domesticated species

2.3.1. Fish and other marine species

2.3.1.1 Fish

2.3.1.2 Marine mammals

2.3.2. Cattle and swine

2.3.3. Chickens

2.4. Immunotoxicity of environmental chemicals in humans

2.4.1. Case reports

2.4.2. Air pollutants

2.4.3. Pesticides

2.4.4. Halogenated aromatic hydrocarbons

2.4.5. Metals

2.4.6. Solvents

2.4.7. Ultraviolet radiation

2.4.8. Others

3. STRATEGIES FOR TESTING THE IMMUNOTOXICITY OF CHEMICALS IN ANIMALS

3.1. General testing of the toxicity of chemicals

3.2. Organization of tests in tiers

3.2.1. US National Toxicology Program panel

3.2.2. Dutch National Institute of Public Health and

Environmental Protection panel

3.2.3. US Environmental Protection Agency, Office of

Pesticides panel

3.2.4. US Food and Drug Administration, Center for Food

Safety and Applied Nutrition panel

3.3. Considerations in evaluating systemic and local

immunotoxicity

3.3.1. Species selection

3.3.2. Systemic immunosuppression

3.3.3. Local suppression

4. METHODS OF IMMUNOTOXICOLOGY IN EXPERIMENTAL ANIMALS

4.1. Nonfunctional tests

4.1.1. Organ weights

4.1.2. Pathology

4.1.3. Basal immunoglobulin level

4.1.4. Bone marrow

4.1.5. Enumeration of leukocytes in bronchoalveolar lavage

fluid, peritoneal cavity, and skin

4.1.6. Flow cytometric analysis

4.2. Functional tests

4.2.1. Macrophage activity

4.2.2. Natural killer activity

4.2.3. Antigen-specific antibody responses

4.2.4. Antibody responses to sheep red blood cells

4.2.4.1 Spleen immunoglobulin M and

immunoglobulin G plaque-forming cell

assay to the T-dependent antigen, sheep

red blood cells

4.2.4.2 Enzyme-linked immunosorbent assay of

anti-sheep red blood cell antibodies of

classes M, G, and A in rats

4.2.5. Responsiveness to B-cell mitogens

4.2.6. Responsiveness to T-cell mitogens

4.2.7. Mixed lymphocyte reaction

4.2.8. Cytotoxic T lymphocyte assay

4.2.9. Delayed-type hypersensitivity responses

4.2.10. Host resistance models

4.2.10.1 Listeria monocytogenes

4.2.10.2 Streptococcus infectivity models

4.2.10.3 Viral infection model with mouse and rat

cytomegalovirus

4.2.10.4 Influenza virus model

4.2.10.5 Parasitic infection model with

Trichinella spiralis

4.2.10.6 Plasmodium model

4.2.10.7 B16F10 Melanoma model

4.2.10.8 PYB6 Carcinoma model

4.2.10.9 MADB106 Adenocarcinoma model

4.2.11. Autoimmune models

4.3. Assessment of immunotoxicity in non-rodent species

4.3.1. Non-human primates

4.3.2. Dogs

4.3.3. Non-mammalian species

4.3.3.1 Fish

4.3.3.2 Chickens

4.4. Approaches to assessing immunosuppression in vitro

4.5. Future directions

4.5.1. Molecular approaches in immunotoxicology

4.5.2. Transgenic mice

4.5.3. Severe combined immunodeficient mice

4.6. Biomarkers in epidemiological studies and monitoring

4.7. Quality assurance for immunotoxicology studies

4.8. Validation

5. ESSENTIALS OF IMMUNOTOXICITY ASSESSMENT IN HUMANS

5.1. Introduction: Immunocompetence and immunosuppression

5.2. Considerations in assessing human immune status related to

immunotoxicity

5.3. Confounding variables

5.4. Considerations in the design of epidemiological studies

5.5. Proposed testing regimen

5.6. Assays for assessing immune status

5.6.1. Total blood count and differential

5.6.2. Tests of the antibody-mediated immune system

5.6.2.1 Immunoglobulin concentration

5.6.2.2 Specific antibodies

5.6.3. Tests for inflammation and autoantibodies

5.6.3.1 C-Reactive protein

5.6.3.2 Antinuclear antibody

5.6.3.3 Rheumatoid factor

5.6.3.4 Thyroglobulin antibody

5.6.4. Tests for cellular immunity

5.6.4.1 Flow cytometry

5.6.4.2 Delayed-type hypersensitivity

5.6.4.3 Proliferation of mononuclear cells in vitro

5.6.5. Tests for nonspecific immunity

5.6.5.1 Natural killer cells

5.6.5.2 Polymorphonuclear granulocytes

5.6.5.3 Complement

5.6.6. Clinical chemistry

5.6.7. Additional confirmatory tests

6. RISK ASSESSMENT

6.1. Introduction

6.2. Complements to extrapolating experimental data

6.2.1. In-vitro approaches

6.2.2. Parallellograms

6.2.3. Severe combined immunodeficient mice

6.3. Host resistance and clinical disease

7. SOME TERMS USED IN IMMUNOTOXICOLOGY

ABBREVIATIONS

ACTH adrenocorticotrophic hormone

Ah aromatic hydrocarbon

AIDS acquired immunodeficiency syndrome

B bursa-dependent

CALLA common acute lymphoblastic leukaemia antigen

CD cluster of differentiation

CEC Commission of the European Communities

CH50 haemolytic complement

CML cell-mediated lympholysis

DMBA 7,12-dimethylbenz[ a]anthracene

DNCB dinitrochlorobenzene

ELISA enzyme-linked immunosorbent assay

EPO erythrocyte lineage differentiation factor

FACS fluorescence activated cell sorter

GALT gut-associated lymphoid tissue

G-CSF granulocyte colony-stimulating factor

GM-CSF granulocyte-macrophage colony-stimulating factor

GVH graft-versus-host

HCB hexaclorobenzene

HEV high endothelial venule

HIV human immunodeficiency virus

HPCA human progenitor cell antigen

HSA heat-stable antigen

ICAM intercellular adhesion molecule

IFN interferon

Ig immunoglobulin

IL interleukin

IPCS International Programme on Chemical Safety

LFA lymphocyte function-related antigen

LIF leukaemia inhibitory factor

LOAEL lowest-observed-adverse-effect level

LOEL lowest-observed-effect level

M microfold

MALT mucosa-associated lymphoid tissue

MARE monoclonal anti-rat immunoglobulin E

MARK monoclonal antibody anti-kappa

M-CSF macrophage colony-stimulating factor

MED minimal erythemal dose

MHC major histocompatibility complex

NCAM neural cell adhesion molecule

NK natural killer

NOAEL no-observed-adverse-effect level

NOEL no-observed-effect level

NTP National Toxicology Program

PAH polycyclic aromatic hydrocarbon

PCB polychlorinated biphenyl

PG prostaglandin

QCA quiescent cell antigen

RIVM Dutch National Institute of Public Health and

Environmental Protection

S9 9000 x g supernatant

SCF stem-cell factor

SCID severe combined immunodeficiency

SIS skin immune system

STM Salmonella typhimurium mitogen

TBTO tri- n-butyltin oxide

Tc cytotoxic T cell

TCDD 2,3,7,8-tetrachlorodibenzo- para-dioxin

TCR T-cell receptor

Tdth delayed-type hypersensitivity T cell

TGF transforming growth factor

Th T helper-inducer cell

THAM T-cell activation molecule

THI 2-acetyl-4(5)-tetrahydroxybutylimidazole

O,O,S-TMP O,O,S-trimethylphosphorothiate

TNF tumour necrosis factor

UVB ultraviolet B

UVR ultraviolet radiation

VCAM vascular cell adhesion molecule

VLA very late antigen

1. INTRODUCTION TO IMMUNOTOXICOLOGY

1.1 Historical overview

It is well established that each individual has an intrinsic capacity to defend itself against pathogens in the environment, with a defence known as the immune system. By general definition, the immune system serves the body by neutralizating, inactivating, or eliminating potentially pathogenic invaders such as microorganisms (bacteria and viruses); it also guards against uncontrolled growth of cells into neoplasms, or tumours. The major features of the structure and function of the immune system have been elucidated over the last three decades; in parallel, awareness grew of toxicological manifestations after exposure to xenobiotic chemicals.

Immunotoxicology is the study of the interactions of chemicals and drugs with the immune system. A major focus of immunotoxicology is the detection and evaluation of undesired effects of substances by means of tests on rodents. The prime concern is to assess the importance of these interactions in regard to human health. Toxic responses may occur when the immune system is the target of chemical insults, resulting in altered immune function; this in turn can result in decreased resistance to infection, certain forms of neoplasia, or immune dysregulation or stimulation which exacerbates allergy or autoimmunity. Alternatively, toxicity may arise when the immune system responds to the antigenic specificity of the chemical as part of a specific immune response (i.e. allergy or autoimmunity). Certain drugs induce autoimmunity (Kammüller et al., 1989; Kammüller & Bloksma,1994). The differentiation between direct toxicity and toxicity due to an immune response to a compound is to a certain extent artificial. Some compounds can exert a direct toxic action on the immune system as well as altering the immune response. Heavy metals like lead an mercury, for instance, manifest immunosuppressive activity,

hypersensitivity, and autoimmunity (Lawrence et al., 1987). Toxicological research over the past decade has indicated that the immune system is a potential 'target organ' for toxic damage. This finding was the basis for a number of large scientific conferences on immunotoxicology and sparked the active interest of national and international organizations in this field.

Table 1. Examples of compounds that are immunotoxic for humans or rodents

Chemical Immune toxicity

-------------------

Rodent Human

2,3,7,8-Tetrachlorodibenzo-para-dioxin + +

Polychlorinated biphenyls + +

Polybrominated biphenyls + +

Hexachlorobenzene + Unknown

Lead + Unknown

Cadmium + Unknown

Methyl mercury compounds + Unknown

7,12-Dimethylbenz[a]anthracene + Unknown

Benzo[a]pyrene + Unknown

Di-n-octyltindichloride + Unknown

Di-n-butyltindichloride + Unknown

Benzidine + +

Nitrogen dioxide and ozone + +

Benzene, toluene, and xylene + +

Asbestos + +

N-Nitrosodimethylamine + Unknown

Diethylstilboestrol + +

Vanadium + +

1.2 The immune system: functions, system regulation, and modifying

factors; histophysiology of lymphoid organs

1.2.1 Function of the immune system

In order to interpret pathological alterations of the immune system in terms of altered function, the physiology of the system mus be understood. Since knowledge of the structure and function of the immune system is growing rapidly.

2.2 Direct immunotoxicity in laboratory animals

The following are some illustrative examples of immunotoxic

chemicals.

2.2.1 Azathioprine and cyclosporin A

The immunosuppressive effects of azathioprine and cyclosporin A

are considered because they can shed light on the direct

immunotoxicity of environmental chemicals.

2.2.1.1 Azathioprine

Azathioprine is a thiopurine that is used as cytostatic drug in

the treatment of leukaemias and as an immunosuppressant in patients

who have received allogeneic organ transplants or who have autoimmune

diseases. When used as an immunosuppressant, its main side-effect is

bone-marrow depression, reflected in blood leukocytopenia; its

administration must therefore be monitored through blood leukocyte

counts. Another side-effect, especially after long-term

administration, is tumour formation (IARC, 1987).

In rats, azathioprine is cytotoxic for all cell lineages in the

bone marrow, and strong cellular depletion is observed histologically.

It decreases the cellularity in thymus, blood, and peripheral lymphoid

organs, but it is mainly in the thymus that the immature lymphocyte

population of the cortex is affected. This effect is a general feature

of most cytostatic drugs. A similar effect is seen in the thymus after

treatment with glucocorticosteroids, but the molecular mechanism

resulting in lymphocyte depletion is obviously different: interference

with DNA synthesis resulting in lymphocyte proliferation in contrast

to binding to glucocorticosteroid receptors and cell down-modulation.

Azathioprine affects a number of indicators of immune function, like

macrophage cytotoxicity (Spreafico et al., 1987), lymphocyte

proliferation in vitro after mitogen stimulation (Weissgarten et

al., 1989) and in the mixed leukocyte reaction (Mellert et al., 1989),

and cytotoxicity by NK cells (Pedersen & Beyer, 1986; Spreafico et

al., 1987; Versluis et al., 1989). Both stimulation and suppression of

these functions have been found in experimental animals, depending on

the dosage and the time of testing after exposure. These findings are

in accordance with those in azathioprine-treated patients, who showed

no change in primary antibody response, a decrease in secondary

antibody response, and some or no effect on lymphocyte proliferation

in vitro after mitogen stimulation. The time of testing after the

start of exposure to azathioprine was a crucial factor in the

detection of effects. Azathioprine was tested in the IPCS-European

Union international collaborative immunotoxicity study (see section

1.1) and showed a significant strain-dependent sensitivity.

2.2.1.2 Cyclosporin A

Cyclosporin A is one of the most powerful immunosuppressive drugs

(Kahan, 1989). It is a neutral lipophilic cyclic peptide consisting of

11 amino acids (relative molecular mass, 1203 Da) isolated from the

fungus Tolypocladium inflatum. Its main use is in bone-marrow

transplantation to prevent transplant rejection and graft-versus-host

reactions. It is also used in the therapy of various autoimmune

diseases.

A complication of cyclosporin A treatment is nephrotoxicity.

Another side-effect, especially after long-term administration, is

tumour formation (IARC, 1987). In its immunosuppressive action,

cyclosporin A does not affect resting lymphocytes but blocks the

events occurring after stimulation, particularly the synthesis of

lymphokines, including IL-1 and IL-2, and IL-2 receptors. The

synthesis of IL-1 by antigen-presenting cells and of IL-2 by Th cells

is inhibited, and the synthesis of IFN gamma and tumour necrosis

factor is blocked. These events occur inside the cell at the

transcriptional level. Cyclosporin A binds to an intracellular

receptor, cyclophilin, forming a complex with calcineurin; this

complex in turn interferes with the activation of genes, resulting in

inhibition of lymphokine gene transcription (Baumann et al., 1992;

Sigal & Dumont, 1992).

An interesting feature of cyclosporin A is its specific action on

the thymus and the induction of autoimmune phenomena. Rats treated

with total body irradiation and syngeneic or autologous bone-marrow

transplantation, followed by treatment with cyclosporin A at a dose of

about 10 mg/kg body weight per day subcutaneously for four weeks,

developed signs of acute graft-versus-host reactions, with lymphocytic

infiltration at multiple epithelial sites (Glazier et al., 1983). A

similar pseudo-graft-versus-host reaction has also been evoked in

mice. It is associated with thymic changes, because it can be

transferred in whole thymus or thymocytes (Sakaguchi & Sakaguchi,

1988). Histologically, the medullary area is diminished (Beschorner et

al., 1987a; Schuurman et al., 1990; see also Figure 21). The medullary

stroma shows a decrease in MHC class II expression, indicating a loss